If a variant has more than one submission, it may be counted in more than one significance column. If this is the
case, the total number of variants will be less than the sum of the other cells.
Gene and significance breakdown #
Total genes and gene combinations: 102
| Gene or gene combination |
pathogenic |
likely pathogenic |
uncertain significance |
likely benign |
benign |
not provided |
total |
|
DNAH5
|
675
|
361
|
1764
|
3377
|
304
|
0 |
5808
|
|
DNAH11
|
376
|
113
|
1467
|
3050
|
1204
|
0 |
5581
|
|
DNAH8
|
118
|
32
|
796
|
893
|
147
|
1
|
1985
|
|
RPGR
|
367
|
21
|
462
|
347
|
81
|
0 |
1244
|
|
DNAI1
|
106
|
82
|
306
|
541
|
27
|
0 |
1001
|
|
CCDC40
|
73
|
22
|
433
|
384
|
78
|
0 |
946
|
|
DNAI2
|
89
|
54
|
269
|
467
|
38
|
0 |
848
|
|
CCDC39
|
118
|
26
|
201
|
333
|
27
|
0 |
680
|
|
DNAAF1
|
44
|
5
|
322
|
238
|
54
|
0 |
630
|
|
DNAAF5
|
29
|
7
|
249
|
299
|
36
|
0 |
596
|
|
ODAD1
|
20
|
10
|
274
|
234
|
46
|
0 |
562
|
|
DNAAF2
|
28
|
2
|
271
|
200
|
25
|
0 |
505
|
|
DNAAF3
|
32
|
11
|
230
|
203
|
27
|
0 |
484
|
|
DRC1
|
24
|
4
|
167
|
208
|
29
|
0 |
432
|
|
RSPH4A
|
38
|
11
|
189
|
104
|
20
|
0 |
348
|
|
ODAD2
|
5
|
2
|
198
|
69
|
19
|
0 |
293
|
|
ZMYND10
|
19
|
5
|
86
|
107
|
12
|
0 |
229
|
|
DNAH11, LOC126859961
|
16
|
3
|
52
|
95
|
58
|
0 |
201
|
|
OFD1
|
12
|
4
|
99
|
73
|
15
|
0 |
201
|
|
RSPH9
|
12
|
6
|
89
|
70
|
7
|
0 |
180
|
|
CCNO
|
17
|
4
|
68
|
82
|
8
|
0 |
179
|
|
RSPH1
|
17
|
6
|
64
|
75
|
18
|
0 |
178
|
|
CCDC39, TTC14
|
18
|
2
|
55
|
87
|
11
|
0 |
169
|
|
SPAG1
|
4
|
4
|
102
|
41
|
13
|
0 |
163
|
|
NME8
|
0 |
0 |
104
|
40
|
16
|
0 |
160
|
|
MCIDAS
|
8
|
5
|
40
|
99
|
8
|
0 |
159
|
|
DNAAF19
|
17
|
5
|
57
|
77
|
3
|
0 |
153
|
|
CDCA7L, DNAH11
|
36
|
3
|
42
|
54
|
9
|
0 |
138
|
|
DNAAF11
|
10
|
3
|
79
|
25
|
12
|
0 |
128
|
|
DNAAF5, PRKAR1B
|
10
|
1
|
59
|
46
|
0 |
0 |
114
|
|
DNAH8, LOC126859667
|
3
|
0 |
33
|
43
|
1
|
0 |
80
|
|
DNAAF2, LOC130055542
|
9
|
0 |
36
|
27
|
2
|
1
|
74
|
|
DNAH5, LOC107457585
|
7
|
1
|
28
|
41
|
3
|
0 |
74
|
|
DNAAF5, LOC129997730, PRKAR1B
|
3
|
0 |
34
|
29
|
1
|
0 |
66
|
|
DNAH5, LOC126807318
|
2
|
2
|
18
|
41
|
3
|
0 |
60
|
|
LOC126653391, RSPH1
|
2
|
0 |
10
|
30
|
1
|
0 |
43
|
|
LOC130000832, SPAG1
|
1
|
0 |
23
|
10
|
2
|
0 |
36
|
|
DNAH1
|
1
|
4
|
24
|
0 |
0 |
0 |
29
|
|
DNAAF5, LOC129997731, PRKAR1B
|
2
|
0 |
13
|
14
|
0 |
0 |
27
|
|
LOC126860891, ODAD2
|
0 |
0 |
16
|
9
|
1
|
0 |
26
|
|
DNAH11, LOC126859962
|
3
|
0 |
2
|
14
|
7
|
0 |
24
|
|
CCNO, LOC129993895
|
8
|
2
|
6
|
8
|
0 |
0 |
22
|
|
DNAAF3, LOC130065090
|
3
|
1
|
11
|
6
|
2
|
0 |
21
|
|
LOC129997052, RSPH4A
|
2
|
1
|
13
|
5
|
1
|
0 |
21
|
|
LOC132089773, ODAD2
|
0 |
0 |
12
|
2
|
2
|
0 |
16
|
|
LOC129993892, MCIDAS
|
1
|
0 |
6
|
7
|
0 |
0 |
14
|
|
LOC130068098, RPGR
|
5
|
0 |
2
|
5
|
2
|
0 |
14
|
|
DNAAF2, LOC130055541
|
1
|
0 |
6
|
4
|
1
|
0 |
12
|
|
DNAAF4, DNAAF4-CCPG1
|
8
|
2
|
3
|
0 |
0 |
0 |
12
|
|
DNAH8, LOC126859668
|
0 |
1
|
6
|
3
|
1
|
0 |
11
|
|
DNAH9
|
0 |
1
|
8
|
0 |
0 |
0 |
9
|
|
DAW1
|
5
|
0 |
0 |
0 |
0 |
0 |
5
|
|
LOC126863212, OFD1
|
0 |
0 |
4
|
1
|
0 |
0 |
5
|
|
OTC, RPGR
|
2
|
0 |
3
|
0 |
0 |
0 |
5
|
|
ODAD3
|
0 |
1
|
3
|
0 |
0 |
0 |
4
|
|
DNAAF1, TAF1C
|
3
|
0 |
0 |
0 |
0 |
0 |
3
|
|
DNAAF3, TNNI3
|
0 |
0 |
2
|
0 |
1
|
0 |
3
|
|
DNAL1
|
1
|
2
|
0 |
0 |
0 |
0 |
3
|
|
DRC2
|
0 |
1
|
2
|
0 |
0 |
0 |
3
|
|
LOC129997051, RSPH4A
|
0 |
0 |
3
|
0 |
0 |
0 |
3
|
|
LOC130066749, RSPH1
|
2
|
0 |
0 |
1
|
0 |
0 |
3
|
|
AGPAT3, CBS, CRYAA, CSTB, GATD3, HSF2BP, NDUFV3, PDE9A, PDXK, PKNOX1, PWP2, RRP1, RRP1B, RSPH1, SIK1, SLC37A1, TRAPPC10, U2AF1, WDR4
|
1
|
0 |
1
|
0 |
0 |
0 |
2
|
|
CCDC40, MIR1268B
|
0 |
0 |
2
|
0 |
0 |
0 |
2
|
|
CFAP221
|
0 |
2
|
0 |
0 |
0 |
0 |
2
|
|
DNAAF5, LOC129997732, PRKAR1B
|
0 |
0 |
0 |
2
|
0 |
0 |
2
|
|
HYDIN
|
2
|
0 |
0 |
0 |
0 |
0 |
2
|
|
RSPH3
|
0 |
0 |
2
|
0 |
0 |
0 |
2
|
|
SPEF2
|
1
|
1
|
0 |
0 |
0 |
0 |
2
|
|
ABCG1, ADARB1, AGPAT3, AIRE, C21orf58, C2CD2, CBS, CFAP410, COL18A1, COL6A1, COL6A2, CRYAA, CSTB, DNMT3L, FTCD, GATD3, HSF2BP, ICOSLG, ITGB2, KRTAP10-1, KRTAP10-10, KRTAP10-11, KRTAP10-12, KRTAP10-2, KRTAP10-3, KRTAP10-4, KRTAP10-5, KRTAP10-6, KRTAP10-7, KRTAP10-8, KRTAP10-9, KRTAP12-1, KRTAP12-2, KRTAP12-3, KRTAP12-4, LINC00163, LINC00315, LINC00334, LRRC3, LSS, MCM3AP, NDUFV3, PCBP3, PCNT, PDE9A, PDXK, PFKL, PKNOX1, POFUT2, PRDM15, PTTG1IP, PWP2, RIPK4, RRP1, RRP1B, RSPH1, SIK1, SLC19A1, SLC37A1, SLX9, SPATC1L, SUMO3, TFF1, TFF2, TFF3, TMPRSS3, TRAPPC10, TRPM2, TSPEAR, U2AF1, UBASH3A, UBE2G2, UMODL1, WDR4, YBEY, ZBTB21
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
AK7
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
ANKRD18B, APTX, AQP3, AQP7, ARHGEF39, ARID3C, ATOSB, B4GALT1, BAG1, CA9, CCDC107, CCIN, CCL19, CCL21, CCL27, CD72, CHMP5, CIMIP2B, CLTA, CNTFR, CREB3, DCAF12, DCTN3, DNAI1, DNAJA1, DNAJB5, ENHO, EXOSC3, FAM219A, FAM221B, FANCG, FBXO10, FRMPD1, GALT, GBA2, GLIPR2, GNE, GRHPR, HINT2, HRCT1, IL11RA, KIF24, MELK, MSMP, MYORG, NDUFB6, NFX1, NOL6, NPR2, NUDT2, OR13J1, OR2S2, PAX5, PHF24, PIGO, POLR1E, PRSS3, RECK, RGP1, RIGI, RMRP, RNF38, RPP25L, RUSC2, SIGMAR1, SIT1, SMU1, SPAG8, SPATA31F1, SPATA31G1, SPINK4, SPMIP6, STOML2, TAF1L, TESK1, TLN1, TMEM215, TMEM8B, TOMM5, TOPORS, TPM2, TRMT10B, UBAP1, UBAP2, UBE2R2, UNC13B, VCP, ZBTB5, ZCCHC7
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
CACNA2D2, CAMKV, CYB561D2, GNAI2, GNAT1, HYAL1, HYAL2, HYAL3, IFRD2, LSMEM2, MON1A, MST1R, NAA80, NPRL2, RASSF1, RBM5, RBM6, SEMA3B, SEMA3F, SLC38A3, TMEM115, TRAIP, TUSC2, ZMYND10
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
CBS, CRYAA, ERVH48-1, FRGCA, LINC01668, LINC01671, LOC101928212, LOC110121500, LOC125418078, LOC125418079, LOC126653391, LOC126653392, LOC129391248, LOC130066747, LOC130066748, LOC130066749, LOC130066750, LOC130066751, LOC130066752, LOC130066753, LOC130066754, LOC130066755, LOC130066756, LOC130066757, LOC130066758, LOC130066759, LOC130066760, LOC130066761, LOC130066762, LOC130066763, LOC130066764, LOC130066765, LOC130066766, LOC130066767, LOC130066768, LOC130066769, LOC130066770, MIR5692B, NDUFV3, PDE9A, PKNOX1, RSPH1, RSPH1-DT, SLC37A1, U2AF1, WDR4
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
CCDC39, LOC129937993, LOC129937994
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
CCDC40, GAA
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
CDCA7L, DNAH11, HYCC1, IL6, KLHL7, KLHL7-DT, RAPGEF5, SP4, STEAP1B, TOMM7
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
CDCA7L, DNAH11, HYCC1, IL6, RAPGEF5, SP4, STEAP1B, TOMM7
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
CFAP20DC
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
CFAP221, LOC129934669
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
CFAP300
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
CFAP57, LOC105378685
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
CLDN2, DNAAF6, MORC4, NRK, NUP62CL, PWWP3B, RADX, RBM41, RIPPLY1, RNF128, SERPINA7, TBC1D8B
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
CYBB, DYNLT3, H2AP, OTC, RPGR, SRPX, SYTL5, XK
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
CYBB, DYNLT3, H2AP, RPGR, SRPX, SYTL5, XK
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DNAAF1, HSDL1, MBTPS1, MLYCD, NECAB2, OSGIN1, SLC38A8, TAF1C
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DNAAF19, FAM187A
|
0 |
0 |
0 |
1
|
1
|
0 |
1
|
|
DNAAF2, LRR1, MGAT2, POLE2, RN7SL1, RPL36AL, RPS29
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DNAAF3, LOC130065090, TNNI3
|
0 |
0 |
0 |
1
|
0 |
0 |
1
|
|
DNAAF3, TNNI3, TNNT1
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
DNAAF6
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
DNAH5, TRIO
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DNAH9, LOC126862505
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DNAJB13
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DRC1, LOC129933333
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
DRC4
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
FAM162B, GPRC6A, KPNA5, RFX6, RSPH4A, ZUP1
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
|
GAS2L2
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
KIAA0586
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
LOC130000832, SPAG1, VPS13B
|
0 |
0 |
0 |
1
|
0 |
0 |
1
|
|
NEK10
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
ODAD4
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
RAG1
|
0 |
0 |
1
|
0 |
0 |
0 |
1
|
Submitter and significance breakdown #
| Submitter |
pathogenic |
likely pathogenic |
uncertain significance |
likely benign |
benign |
not provided |
total |
|
Labcorp Genetics (formerly Invitae), Labcorp
|
2302
|
434
|
4815
|
11341
|
2207
|
0 |
21099
|
|
Ambry Genetics
|
185
|
54
|
4241
|
1716
|
518
|
0 |
6714
|
|
Natera, Inc.
|
97
|
271
|
953
|
102
|
103
|
0 |
1526
|
|
UNC Molecular Genetics Laboratory, University of North Carolina at Chapel Hill
|
11
|
32
|
146
|
4
|
0 |
0 |
193
|
|
Yale Center for Mendelian Genomics, Yale University
|
0 |
72
|
0 |
0 |
0 |
0 |
72
|
|
Laboratory for Molecular Medicine, Mass General Brigham Personalized Medicine
|
16
|
16
|
0 |
0 |
0 |
0 |
32
|
|
Department of Genetics, Sultan Qaboos University Hospital
|
14
|
7
|
5
|
0 |
0 |
0 |
26
|
|
Institute Of Molecular Biology And Genetics, Federal Almazov National Medical Research Centre
|
16
|
3
|
3
|
0 |
0 |
0 |
22
|
|
Cambridge Genomics Laboratory, East Genomic Laboratory Hub, NHS Genomic Medicine Service
|
20
|
0 |
0 |
0 |
0 |
0 |
20
|
|
Centre for Genomic and Experimental Medicine, University of Edinburgh
|
9
|
2
|
0 |
0 |
0 |
0 |
11
|
|
Department of Pathology and Laboratory Medicine, Sinai Health System
|
1
|
4
|
1
|
0 |
0 |
0 |
6
|
|
Dubai Health Genomic Medicine Center, Dubai Health
|
4
|
2
|
0 |
0 |
0 |
0 |
6
|
|
Clinical Genetics Laboratory, Skane University Hospital Lund
|
0 |
2
|
3
|
0 |
0 |
0 |
5
|
|
Molecular Genetics, Royal Melbourne Hospital
|
2
|
2
|
1
|
0 |
0 |
0 |
5
|
|
New Leaf Center
|
5
|
0 |
0 |
0 |
0 |
0 |
5
|
|
Genetics and Molecular Pathology, SA Pathology
|
0 |
0 |
4
|
0 |
0 |
0 |
4
|
|
Fulgent Genetics, Fulgent Genetics
|
0 |
0 |
3
|
0 |
0 |
0 |
3
|
|
Center of Genomic medicine, Geneva, University Hospital of Geneva
|
2
|
0 |
0 |
0 |
0 |
0 |
2
|
|
GenomeConnect - Invitae Patient Insights Network
|
0 |
0 |
0 |
0 |
0 |
2
|
2
|
|
Sezerman Lab, Dept of Biostatistics and Bioinformatics, Acibadem Mehmet Ali Aydinlar University
|
2
|
0 |
0 |
0 |
0 |
0 |
2
|
|
The Research Institute of Tuberculosis, Japan Anti-Tuberculosis Association
|
0 |
2
|
0 |
0 |
0 |
0 |
2
|
|
Equipe Genetique des Anomalies du Developpement, Université de Bourgogne
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
Illumina Laboratory Services, Illumina
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
Institute of Reproductive and Stem Cell Engineering, Central South University
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
Laboratory of Medical Genetics, National & Kapodistrian University of Athens
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
MVZ Martinsried, Medicover Genetics
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
Molecular and Clinical Genetics, Institute of Human Genetics P.A.S.
|
1
|
0 |
0 |
0 |
0 |
0 |
1
|
|
NHS Central & South Genomic Laboratory Hub
|
0 |
1
|
0 |
0 |
0 |
0 |
1
|
|
OMIM
|
0 |
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