Total submissions: 3
| Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
|---|---|---|---|---|---|---|---|---|
| Baylor Genetics | RCV003333089 | SCV004041377 | pathogenic | Keratosis linearis-ichthyosis congenita-sclerosing keratoderma syndrome | 2023-08-12 | criteria provided, single submitter | clinical testing | |
| Undiagnosed Diseases Network, |
RCV000663381 | SCV000746565 | pathogenic | Proteasome-associated autoinflammatory syndrome 2 | 2017-02-14 | criteria provided, single submitter | clinical testing | This frameshift mutation is categorized as deleterious according to ACMG guidelines (PMID: 18414213) and was found de novo in a 2-year-old male with seizure-like movements, B-lymphocyte immunodeficiency, thrombocytopenia, anemia, eosinophilia, hypogammaglobulinemia, dermatosis, and skin anomalies suggestive of Sweet syndrome. This individual has been reported in PMID: 29805043 (individual B). |
| OMIM | RCV000663381 | SCV000786664 | pathogenic | Proteasome-associated autoinflammatory syndrome 2 | 2018-07-17 | no assertion criteria provided | literature only |