ClinVar Miner

Submissions for variant NM_002863.5(PYGL):c.1729C>T (p.Gln577Ter)

gnomAD frequency: 0.00010  dbSNP: rs149096315
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Total submissions: 4
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Submitter RCV SCV Clinical significance Condition Last evaluated Review status Method Comment
NHS Central & South Genomic Laboratory Hub RCV006650422 SCV007542571 pathogenic Glycogen storage disease 2026-04-22 criteria provided, single submitter clinical testing
Mayo Clinic Laboratories, Mayo Clinic RCV001585707 SCV007134720 likely pathogenic not provided 2025-12-10 criteria provided, single submitter clinical testing PP1, PM2_supporting, PVS1
GeneDx RCV001585707 SCV001818320 pathogenic not provided 2025-09-10 criteria provided, single submitter clinical testing Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; This variant is associated with the following publications: (PMID: 25266922)
Labcorp Genetics (formerly Invitae), Labcorp RCV000779139 SCV000943489 pathogenic Glycogen storage disease, type VI 2023-11-10 criteria provided, single submitter clinical testing This sequence change creates a premature translational stop signal (p.Gln577*) in the PYGL gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in PYGL are known to be pathogenic (PMID: 9536091, 21646031). This variant is present in population databases (rs149096315, gnomAD 0.01%). This premature translational stop signal has been observed in individual(s) with glycogen storage disease type VI (PMID: 25266922). ClinVar contains an entry for this variant (Variation ID: 632216). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. For these reasons, this variant has been classified as Pathogenic.

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