ClinVar Miner

Submissions for variant NM_001267550.2(TTN):c.67147G>A (p.Gly22383Arg)

gnomAD frequency: 0.00004  dbSNP: rs372388682
Minimum review status: Collection method:
Minimum conflict level:
ClinVar version:
Total submissions: 7
Download table as spreadsheet
Submitter RCV SCV Clinical significance Condition Last evaluated Review status Method Comment
Genomic Medicine Center of Excellence, King Faisal Specialist Hospital and Research Centre RCV003989305 SCV004808143 uncertain significance Dilated cardiomyopathy 1G 2024-03-29 criteria provided, single submitter clinical testing
Revvity Omics, Revvity RCV001507592 SCV003826009 uncertain significance not provided 2023-08-21 criteria provided, single submitter clinical testing
GeneDx RCV001507592 SCV001813200 likely benign not provided 2019-11-04 criteria provided, single submitter clinical testing This variant is associated with the following publications: (PMID: 25979592, 24503780)
Mayo Clinic Laboratories, Mayo Clinic RCV001507592 SCV001713223 uncertain significance not provided 2020-07-23 criteria provided, single submitter clinical testing
Ambry Genetics RCV000618423 SCV000735154 uncertain significance Cardiovascular phenotype 2019-09-26 criteria provided, single submitter clinical testing The p.G13318R variant (also known as c.39952G>A), located in coding exon 145 of the TTN gene, results from a G to A substitution at nucleotide position 39952. The glycine at codon 13318 is replaced by arginine, an amino acid with dissimilar properties. This variant was reported in one individual with dilated cardiomyopathy (DCM) and in another individual with hypertrophic cardiomyopathy (HCM), both of which also had variants in other cardiac-related genes (Pugh TJ et al. Genet Med. 2014;16(8):601-8 (reported as p.G19815R (c.59443G>A), Waldmüller et al. Mol Cell Probes. 2015 Oct;29(5):308-14 (reported as p.G20742R (c.62224G>A)). This amino acid position is highly conserved in available vertebrate species. In addition, the in silico prediction for this alteration is inconclusive. Since supporting evidence is limited at this time, the clinical significance of this variant remains unclear.
Labcorp Genetics (formerly Invitae), Labcorp RCV000462522 SCV000542317 uncertain significance Dilated cardiomyopathy 1G; Autosomal recessive limb-girdle muscular dystrophy type 2J 2018-01-08 criteria provided, single submitter clinical testing This sequence change replaces glycine with arginine at codon 22383 of the TTN protein (p.Gly22383Arg). There is a moderate physicochemical difference between glycine and arginine. This variant is present in population databases (rs372388682, ExAC 0.02%). This variant has not been reported in the literature in individuals with TTN-related disease. ClinVar contains an entry for this variant (Variation ID: 47249). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site, but this prediction has not been confirmed by published transcriptional studies. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance.
Laboratory for Molecular Medicine, Mass General Brigham Personalized Medicine RCV000040519 SCV000064210 uncertain significance not specified 2012-01-19 criteria provided, single submitter clinical testing The Gly19815Arg variant (TTN) has been identified in 1/6589 European American ch romosomes by the NHLBI Exome Sequencing Project in a broad population (http://ev s.gs.washington.edu/EVS). Computational analyses (biochemical amino acid propert ies, conservation, AlignGVGD and SIFT) do not provide strong support for or agai nst pathogenicity. Additional information is needed to fully assess the clinical significance of the Gly19815Arg variant.

The information on this website is not intended for direct diagnostic use or medical decision-making without review by a genetics professional. Individuals should not change their health behavior solely on the basis of information contained on this website. The submitted information has not been verified. If you have questions about the information contained on this website, please see a health care professional.