ClinVar Miner

Submissions for variant NM_000527.5(LDLR):c.1987+10G>T

gnomAD frequency: 0.00004  dbSNP: rs375846192
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Total submissions: 4
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Submitter RCV SCV Clinical significance Condition Last evaluated Review status Method Comment
ClinGen Familial Hypercholesterolemia Variant Curation Expert Panel RCV000238481 SCV007432528 uncertain significance Hypercholesterolemia, familial, 1 2025-03-24 reviewed by expert panel curation The NM_000527.5(LDLR):c.1987+10G>T variant is classified as Uncertain significance - insufficient evidence for Familial Hypercholesterolemia by applying ACMG/AMP evidence codes PM2, PP4, PS4_Supporting and BP4 as defined by the ClinGen Familial Hypercholesterolemia Expert Panel LDLR-specific variant curation guidelines (specification version 1.2) on 24 March 2025. The supporting evidence is as follows: PM2: PopMax MAF = 0.00008220 (0.00822%) in Non-Finnish European (gnomAD v4.1.0). PS4_Supporting, PP4: Variant meets PM2 and is identified in 2 unrelated cases who fulfill Simon Broome criteria for possible FH from Centre de Génétique Moléculaire et Chromosomique, Unité de génétique de l'Obésité et des Dyslipidémies, APHP.Sorbonne Université, Hôpital de la Pitié-Salpêtrière, France. BP4: No REVEL, splicing evaluation required. SpliceAI: acceptor loss = 0.01, donor loss = 0.04. Variant is not predicted to alter splicing.
Labcorp Genetics (formerly Invitae), Labcorp RCV001505338 SCV001710236 likely benign Familial hypercholesterolemia 2025-04-28 criteria provided, single submitter clinical testing
Women's Health and Genetics/Laboratory Corporation of America, LabCorp RCV005238789 SCV000697218 likely benign not specified 2024-12-12 criteria provided, single submitter clinical testing
LDLR-LOVD, British Heart Foundation RCV000238481 SCV000295795 likely benign Hypercholesterolemia, familial, 1 2016-03-25 criteria provided, single submitter research

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